Year 2021 / Volume 113 / Number 1
Letter
A case of Currarino syndrome in an adult female presenting with refractory chronic constipation

73-74

DOI: 10.17235/reed.2020.7096/2020

Eukene Rojo Aldama, Pablo Miranda García, Javier García Septiem,

Abstract
We present the case of a 25-year-old female who presented due to refractory chronic constipation and fecal incontinence. She had bowel movements every 7-30 days with an increased consistency (1-2 Bristol type stools), together with soiling and passive fecal incontinence (Wexner Scale: 12/20). She had previously undergone surgery shortly after birth for an anorectal malformation repair. The colonoscopy and histological study of the rectum were normal. A pelvic magnetic resonance imaging (MRI) was performed, which showed a right pararectal mass that compressed the rectum without invading it. This mass was compatible with a presacral teratoma or hamartoma. MRI also revealed coccyx agenesis and hypoplasia of the last sacral vertebrae (Image 1), which were consistent with Currarino syndrome (CS). The patient received 14 sessions of transcutaneous electrostimulation of the posterior tibial nerve, resulting in an increase in bowel movements (every 3 days) and a reduction in fecal incontinence. She was then referred to surgery for presacral mass removal.
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References
1.- Caro-Domínguez P, Bass J, Hurteau-Miller J. Currarino syndrome in a fetus, infant, child, and adolescent: spectrum of clinical presentations and imaging findings. Can Assoc Radiol J 2017; 68:90–5.
2.- Crétolle C, Zérah M, Jaubert F, et al. New clinical and therapeutic perspectives in Currarino syndrome (study of 29 cases). J Pediatr Surg 2006; 41:126–31.
3- Chakhalian D, Gunasekaran A, Gandhi G, et al. Multidisciplinary surgical treatment of presacral meningocele and teratoma in an adult with Currarino triad. Surg Neurol Int. 2017; 8:77.
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Rojo Aldama E, Miranda García P, García Septiem J. A case of Currarino syndrome in an adult female presenting with refractory chronic constipation. 7096/2020


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Publication history

Received: 31/03/2020

Accepted: 13/04/2020

Online First: 19/11/2020

Published: 11/01/2021

Article Online First time: 233 days

Article editing time: 286 days


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